Atopic diathesis in hypohidrotic/anhidrotic ectodermal dysplasia.

نویسندگان

  • Hanako Koguchi-Yoshioka
  • Mari Wataya-Kaneda
  • Mizuki Yutani
  • Hiroyuki Murota
  • Hajime Nakano
  • Daisuke Sawamura
  • Ichiro Katayama
چکیده

Recently, patients with hypohidrotic/anhidrotic ectodermal dysplasia (H/AED) have been reported to have a higher prevalence of symptoms suggestive of atopic disorders than the general population. To better understand atopic diathesis in H/AED, 6 cases of clinically or genetically diagnosed H/AED were examined. The following criteria were evaluated with patient consent: sweating, blood test results, histopathology and filaggrin staining. Five of 6 H/AED cases displayed atopic dermatitis-like manifestations, and 3 of these 5 cases experienced periorbital lesions. H/AED patients tended to present with atopic dermatitis-like eruptions with characteristics potentially indicative of periorbital lesions. Atopic diathesis in H/AED appeared not to be associated with filaggrin. We could speculate that hypohidrosis or anhidrosis itself might impair skin barrier function and contribute to atopic diathesis.

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عنوان ژورنال:
  • Acta dermato-venereologica

دوره 95 4  شماره 

صفحات  -

تاریخ انتشار 2015